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Abstract: TH-PO534

Analysis of Peripheral Blood Mononuclear Cells Single-Cell RNA Sequencing Shows IFN Signaling Activation Contributes to the Pathogenesis of Childhood Nephrotic Syndrome

Session Information

Category: Glomerular Diseases

  • 1401 Glomerular Diseases: Mechanisms, including Podocyte Biology

Authors

  • Li, Qiu-yu, Zhejiang University School of Medicine Children's Hospital, Hangzhou, Zhejiang, China
  • Liu, Fei, Zhejiang University School of Medicine Children's Hospital, Hangzhou, Zhejiang, China
  • Kang, Minchao, Zhejiang University School of Medicine Children's Hospital, Hangzhou, Zhejiang, China
  • Bai, Linnan, Zhejiang University School of Medicine Children's Hospital, Hangzhou, Zhejiang, China
  • Wu, Junnan, Zhejiang University School of Medicine Children's Hospital, Hangzhou, Zhejiang, China
  • Mao, Jianhua, Zhejiang University School of Medicine Children's Hospital, Hangzhou, Zhejiang, China
Background

Idiopathic Nephrotic syndrome (INS) is a prevalent glomerular disease, especially in children. Previous understanding of INS pathogenesis has emphasized T-cell changes and their correlation with cytokine shifts. Accumulating evidence indicates that B-cell dysfunction is also involved in the process. Nevertheless, a gap remains in the comprehensive understanding of the mechanisms and cellular interactions among immune cells in new-onset INS.

Methods

Our study employed single-cell RNA sequencing (scRNA-seq) to characterize immuno-dysfunction in peripheral blood mononuclear cells (PBMCs) obtained from five new-onset INS patients before treatment and post-remission, alongside healthy controls. We identified differentially expressed genes and investigated cell-cell communications across different cell types. We also performed validations.

Results

Through differentially expressed gene analysis across clusters, we observed the activation of interferon-stimulated genes (ISGs) and the enrichment of interferon (IFN)-related pathways. Specifically, we noted increased expression of B-cell activating factor (BAFF) in untreated patients, along with elevated expression of BAFF receptors, particularly B-cell maturation antigen (BCMA) in plasma cells, collaborated by flow cytometry in an independent INS cohort. Furthermore, we identified an increase in the serum level of IFN-γ rather than IFN-α.

Conclusion

Our research provides the first comprehensive exploration of IFN-related pathways in the initiation of INS. These results suggest that IFN-γ activation stimulates the interaction between BAFF and B-cell receptors, triggering autoantibody release and contributing to INS pathogenesis. New insights into the pathogenesis of NS may pave the way for precise therapeutic interventions that target these pathways.